Research & Validation

Tools & Scientific References

Peer-reviewed publications for the bioinformatics tools, databases, and guidelines that power the ATGC Flow pipeline

See how these methods are applied in our platform & pipeline specs, or start from the fundamentals in the Genomics Knowledge Base.

Featured Publication

Standards and Guidelines for the Interpretation of Sequence Variants (ACMG/AMP 2015)

Richards S, Aziz N, Bale S, Bick D, Das S, Gastier-Foster J, et al.Genetics in Medicine2015

The American College of Medical Genetics and Genomics and the Association for Molecular Pathology jointly developed updated standards and guidelines for the clinical interpretation of sequence variants. This document establishes the 5-tier classification system (Pathogenic, Likely Pathogenic, VUS, Likely Benign, Benign) with evidence criteria (PVS1, PS1–PS4, PM1–PM6, PP1–PP5, BA1, BS1–BS4, BP1–BP7) that underpins all modern variant interpretation, including the automated ACMG classification engine in ATGC Flow.

14800
Citations
High Impact
Genetics in Medicine

All References

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methodology
14800
citations

Standards and Guidelines for the Interpretation of Sequence Variants (ACMG/AMP 2015)

Richards S, Aziz N, Bale S, Bick D, Das S, Gastier-Foster J, et al.
Genetics in Medicine2015

The American College of Medical Genetics and Genomics and the Association for Molecular Pathology jointly developed updated standards and guidelines for the clinical interpretation of sequence variants. This document establishes the 5-tier classification system (Pathogenic, Likely Pathogenic, VUS, Likely Benign, Benign) with evidence criteria (PVS1, PS1–PS4, PM1–PM6, PP1–PP5, BA1, BS1–BS4, BP1–BP7) that underpins all modern variant interpretation, including the automated ACMG classification engine in ATGC Flow.

methodology
18900
citations

A framework for variation discovery and genotyping using next-generation DNA sequencing data (GATK)

DePristo MA, Banks E, Poplin R, Garimella KV, Maguire JR, Hartl C, et al.
Nature Genetics2011

Describes the Genome Analysis Toolkit (GATK) framework for discovery and genotyping of SNPs and indels from next-generation sequencing data. Introduces the concept of Base Quality Score Recalibration (BQSR) and the HaplotypeCaller variant caller. GATK 4.x is the variant calling backbone of the ATGC Flow pipeline, implementing HaplotypeCaller in GVCF mode for germline variant discovery.

methodology
44000
citations

Fast and accurate short read alignment with Burrows-Wheeler Aligner (BWA-MEM)

Li H, Durbin R
Bioinformatics2010

Presents BWA-MEM, the short-read alignment algorithm that maps sequences against a large reference genome with low divergence. BWA-MEM supports gapped alignment for short-read paired-end sequencing and achieves better performance than alternative algorithms. BWA-MEM2 (the successor) is used in ATGC Flow for aligning FASTQ reads to the GRCh38 reference genome.

methodology
12500
citations

ANNOVAR: Functional annotation of genetic variants from high-throughput sequencing data

Wang K, Li M, Hakonarson H
Nucleic Acids Research2010

Introduces ANNOVAR, an efficient software tool for functional annotation of genetic variants detected from diverse genomes including human exome and genome sequencing. Supports gene-based, region-based and filter-based annotation strategies using locally downloaded databases. ATGC Flow uses ANNOVAR to annotate variants with gene function, population frequencies (gnomAD), pathogenicity scores (dbNSFP), and clinical significance (ClinVar).

methodology
6800
citations

The Ensembl Variant Effect Predictor (VEP)

McLaren W, Gil L, Hunt SE, Riat HS, Ritchie GR, Thormann A, et al.
Genome Biology2016

Describes VEP, Ensembl's variant annotation and effect prediction tool. VEP determines the effect of variants (SNPs, insertions, deletions, CNVs, structural variants) on genes, transcripts, and protein sequence, as well as regulatory regions. VEP v113 is integrated into the ATGC Flow pipeline for HGVS nomenclature generation, consequence prediction, and population frequency annotation.

validation
7200
citations

The mutational constraint spectrum quantified from variation in 141,456 humans (gnomAD)

Karczewski KJ, Francioli LC, Tiao G, Cummings BB, Alföldi J, Wang Q, et al.
Nature2020

Presents the Genome Aggregation Database (gnomAD) v2.1 containing 125,748 exomes and 15,708 genomes from unrelated individuals. Provides allele frequency data across 8 population groups used to filter common variants in disease studies. ATGC Flow uses gnomAD v4.1 (807,162 exomes + 76,215 genomes) as the primary allele frequency filter for rare variant prioritization, applying the PM2 ACMG criterion for variants absent from gnomAD.

methodology
8900
citations

fastp: an ultra-fast all-in-one FASTQ preprocessor

Chen S, Zhou Y, Chen Y, Gu J
Bioinformatics2018

Presents fastp, a tool for quality control, adapter trimming, and filtering of FASTQ files. fastp is 2–4× faster than Trimmomatic, automatically detects adapter sequences for paired-end data, and generates built-in JSON and HTML QC reports. ATGC Flow uses fastp as the first pipeline step for quality control and adapter trimming before alignment.

methodology
4200
citations

Nextflow enables reproducible computational workflows

Di Tommaso P, Chatzou M, Floden EW, Barja PP, Palumbo E, Notredame C
Nature Biotechnology2017

Describes Nextflow, a workflow system for creating scalable, portable, and reproducible computational pipelines. Nextflow DSL2 supports modular pipeline design and seamless execution across local, HPC, and cloud environments using Docker/Singularity containers. ATGC Flow's entire bioinformatics pipeline is built with Nextflow DSL2, enabling reproducible execution from FASTQ to annotated VCF.

validation
3100
citations

A universal SNP and small-indel variant caller using deep neural networks (DeepVariant)

Poplin R, Chang PC, Alexander D, Schwartz S, Colthurst T, Ku A, et al.
Nature Biotechnology2018

Presents DeepVariant, a variant caller that uses a convolutional neural network trained on pileup images of aligned reads to classify SNPs and indels. DeepVariant achieves >99.9% F1 score on SNPs and outperforms GATK HaplotypeCaller on indels in several benchmarks. ATGC Flow supports DeepVariant as an alternative variant caller for Illumina WES data.

validation
1800
citations

dbNSFP v4: a comprehensive database of transcript-specific functional predictions and annotations for human nonsynonymous and splice-site SNVs

Liu X, Li C, Mou C, Dong Y, Tu Y
Genome Medicine2020

Describes dbNSFP v4, a database that compiles functional predictions and annotations from 33 algorithms (SIFT, PolyPhen-2, CADD, REVEL, MetaSVM, etc.) and allele frequencies from multiple population databases for all potential nonsynonymous and splice-site SNVs in the human genome. ATGC Flow incorporates dbNSFP v4.7 to provide in silico pathogenicity evidence for the PP3 and BP4 ACMG criteria.

clinical
5600
citations

ClinVar: improving access to variant interpretations and supporting evidence

Landrum MJ, Lee JM, Benson M, Brown GR, Chao C, Chitipiralla S, et al.
Nucleic Acids Research2018

Describes ClinVar, NCBI's freely accessible archive of human variants and their relationships to human health. ClinVar aggregates submissions from clinical laboratories, research groups, and expert panels and provides classifications with supporting evidence. ATGC Flow queries ClinVar to apply PP5 (reputable source reports variant as pathogenic) and BP6 (reputable source reports variant as benign) ACMG evidence criteria.

Pipeline Components

Open-Source Tools Powering ATGC Flow

Every component of the pipeline is built on peer-reviewed, community-validated bioinformatics software

fastp
Quality control & adapter trimming
Chen et al., Bioinformatics 2018
BWA-MEM2
Short-read alignment to GRCh38
Li & Durbin, Bioinformatics 2010
GATK HaplotypeCaller
Germline variant calling (SNVs & indels)
DePristo et al., Nature Genetics 2011
ANNOVAR + VEP v113
Functional & clinical variant annotation
Wang et al. 2010; McLaren et al. 2016
gnomAD v4.1
Population allele frequency database
Karczewski et al., Nature 2020
ClinVar
Clinical variant classification database
Landrum et al., Nucleic Acids Res. 2018
dbNSFP v4.7
In silico pathogenicity scores (CADD, REVEL, etc.)
Liu et al., Genome Medicine 2020
Nextflow DSL2
Workflow orchestration & reproducibility
Di Tommaso et al., Nature Biotechnology 2017
ACMG/AMP 2015 Guidelines
Variant classification framework
Richards et al., Genetics in Medicine 2015

Acknowledge ATGC Flow

If ATGC Flow contributed to your research or analysis, please acknowledge the software as:

ATGC Flow: Whole Exome Sequencing Analysis Platform [Software] ATGC Flow Team https://atgcflow.com